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VOLUME 14 , ISSUE 2 ( March-April, 2013 ) > List of Articles

CASE REPORT

Sialolithiasis in the Duct of Submandibular Gland: A Case Report in Patient with Epidermolysis Bullosa

Bruno Tochetto Primo, Delson João da Costa, Diego José Stringhini, Nelson Luis Barbosa Rebellato, Rafaela Scariot de Moraes, Paulo Roberto Müller, Vera Lúcia Carneiro

Citation Information : Primo BT, da Costa DJ, Stringhini DJ, Rebellato NL, de Moraes RS, Müller PR, Carneiro VL. Sialolithiasis in the Duct of Submandibular Gland: A Case Report in Patient with Epidermolysis Bullosa. J Contemp Dent Pract 2013; 14 (2):339-344.

DOI: 10.5005/jp-journals-10024-1324

Published Online: 00-04-2013

Copyright Statement:  Copyright © 2013; Jaypee Brothers Medical Publishers (P) Ltd.


Abstract

Aim

To describe the options of treatment to remove a sialolith associated with the submandibular gland duct in a patient with epidermolysis bullosa (EB).

Background

Treatment of patients with EB is very complex and involves a multidisciplinary team. This condition is characterized by a spectrum of blistering and mechanical fragility of the skin. One main feature of this disease is the esophageal constriction and possible constriction to the submandibular duct. This alteration may induce the formation of calculi in this duct, which is called sialolith. Once the sialolith obliterates the trajectory of the duct this will lead to a sialolithiasis. The calculi have to be removed.

Case report

Seventeen years old female patient with dystrophic EB developed a sialolith at the submandibular duct. She has a limited mouth opening and her tongue was collapsed with mouth floor. The first choice of treatment was the lithotripsy, once this procedure is less invasive and a surgical remove could worse the collapsed tongue. She was with acute pain and with a great augmentation in the submandibular area. Once the patient was debilitated and has difficult to swallow she invariably needed to be hospitalized in order to receive intravenous medication. During the hospitalization the sialolith could be seen through the opening of the duct and the calculi was removed with local anesthesia.

Conclusion

The treatment of sialolithiasis usually does not present major challenges, nevertheless if the sialolithiasis is associated with EB, the treatment became an extremely challenge. In this particular case the option of treatment was the less invasive.

Clinical relevance

This case report has an enormous clinical relevance once there is no protocol to treat patients with EB and buccal diseases.

How to cite this article

Primo BT, da Costa DJ, Stringhini DJ, Rebellato NLB, de Moraes RS, Müller PR, Carneiro VL. Sialolithiasis in the Duct of Submandibular Gland: A Case Report in Patient with Epidermolysis Bullosa. J Contemp Dent Pract 2013;14(2):339-344.


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  1. The classification of inherited epidermolysis bullosa (EB): Report of the third international consensus meeting on diagnosis and classification of EB. J Am Acad Dermatol 2008;58:931-50.
  2. Oral Manifestations in the epidermolysis bullosa spectrum. Dermatol Clin 2010;28:159-64.
  3. Revised classification system for inherited epidermolysis bullosa: Report of the second international consensus meeting on diagnosis and classification of epidermolysis bullosa. J Am Acad Dermatol 2000;42:1051-66.
  4. A cephalometric analysis of patients with recessive dystrophic epidermolysis bullosa. Angle Orthod 2002;72:55-60.
  5. Nutrition for children with epidermolysis bullosa. Dermatol Clin 2010;28:289-301.
  6. Oral soft tissues in hereditary epidermolysis bullosa. Oral Surg Oral Med Oral Pathol 1991;71:1184-88.
  7. Oral involvement of recessive dystrophic epidermolysis bullosa inversa. Am J Med Genet 1993;47:1184-88.
  8. Main problems experienced by children epidermolysis bullosa: A qualitative study with semi-structured interviews. Act Derm Venereol 2008;88:143-50.
  9. Medical management of epidermolysis bullosa: Proceedings of the IInd International symposium on epidermolysis Bullosa. Santiago, Chile, 2005. Int J Dermatol 2007;46:795-800.
  10. Pain management in epidermolysis bullosa. Dermatol Clin 2010;28:273-82.
  11. Remove of salivary stones with the lithotriptor. J Cranio Maxillofac Surg 1989;17:329-30.
  12. Shockwave lithotripsy of salivary duct calculi. Lancet 1992;339:1333-36.
  13. Laser lithotripsy: A preliminary study on its application for sialolithiasis. Br J Oral Maxillofac Surg 1994;32:218-21.
  14. Selective management of obstructive submandibular sialadenitis. Br J Oral Maxillofac Surg 2008;46:46-49.
  15. Sialolithiasis of the submandibular gland. J Cranio Maxillofac Surg 2011;22:1128-30.
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